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Author(s):
Yongqiang Ning, Linbu Liao, Lijun Zhang, Xiao Yang, Jie Wang, Qianwen Xie, Yihui Zhang, Rui Li, Qian Liu, Xiling Zhao, Nan Wu, Shancheng Zhao, Jiguang He, Erfei Chen, Ping Gao, Gonghong Wei, Ke Dong, Wenju Sun, Jing Ye, Jian Yan
Publish date:
1 January 2026
Journal:
Genes & Diseases

Abstract

Genome-wide association studies (GWAS) face critical limitations in resolving noncoding variants with functional impacts. Here, we introduce a function-first prioritization strategy that integrates SNP-SELEX-derived transcription factor binding profiles with genetic epidemiology. Applied to type 2 diabetes in the UK Biobank (n = 480,000), this approach identified 305 risk SNPs – 162 novel – with significantly enhanced heritability contribution, with 91 risk SNPs co-localizing at islet enhancers. CEBPB emerged as a master regulator. Focusing on a previously uncharacterized locus (rs2643219), we demonstrated allele-specific CEBPB binding at an intestinal enhancer regulating RASGRP1 – a key effector for insulin-stimulated glucose uptake. CRISPR-mediated knockout of RASGRP1 in intestinal cells ablated GLUT4 translocation and impaired glucose homeostasis in mice. Trans-ethnic validation in a Chinese cohort (n = 1718) confirmed rs2643219’s clinical relevance (OR = 1.30; P = 0.023). Our strategy bridges functional genomics with pathophysiological mechanisms, establishing a blueprint for complex disease variant prioritization.

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Institution:
Northwest University, China

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